TMEM94

Clinical Characteristics

The clinical features of this disease, per organ system, include:

Central Nervous System

  • Global developmental delay
  • Intellectual disability
  • Speech delay
  • Motor delay
  • Generalized hypotonia (some patients)
  • Truncal hypotonia (some patients)
  • Appendicular hypertonia (some patients)
  • Brisk reflexes
  • Ankle clonus
  • Learning disability
  • Seizures (rare)
  • Brain abnormalities (some patients):
    • Symmetrical restricted diffusion
    • High T2 signal intensity of the cerebral white matter and dentate nucleus
    • Chiari malformation
    • Delayed myelination

Head and Neck

  • Macrocephaly (some patients)
  • Microcephaly (rare)
  • Dysmorphic facial features, including:
    • Triangular face
    • Short forehead with low anterior hairline (rare)
    • Pointed chin
    • Dysmorphic ears
    • Low-set ears
    • Prominent ear lobes
    • Posteriorly rotated ears
    • Depressed nasal bridge
    • Anteverted nares
    • Broad nasal bridge
    • Thin upper lip
    • Smooth philtrum
    • Short philtrum (rare)
    • Long philtrum
    • Hypertelorism
    • Deep-set eyes
    • Upslanted palpebral fissures
    • Strabismus
    • Synophrys
    • Thick, arched eyebrows
  • Webbed neck (rare)
  • Long eyelashes (some patients)
  • Myopia (rare)
  • Optic glioma (rare)

Cardiovascular

  • Patent foramen ovale
  • Patent ductus arteriosus
  • Atrial septal defect
  • Ventricular septal defect
  • Pulmonary hypoplasia
  • Pulmonary atresia
  • Tetralogy of Fallot
  • Double outlet right ventricle

Skeletal

  • Scoliosis
  • Long fingers and toes
  • Overlapping fingers and toes
  • Cutaneous syndactyly of the toes
  • Large hands
  • Pectus excavatum (some patients)

Genitourinary

  • Cryptorchidism
  • Hypospadias
  • Late menarche
  • Oligomenorrhea

Other

  • Somatic overgrowth
  • Hypertrichosis
  • Widely spaced nipples
  • Recurrent respiratory infections
  • Dilation of ascending aorta
  • Intraosseous hemangioma
  • Intestinal malrotation
  • Inguinal hernia
  • Omphalocele