FBXW7

Clinical Characteristics

Pathogenic variants in the FBXW7 gene cause a neurodevelopmental disorder with considerable phenotypic heterogeneity.


Most individuals with the mutation FBXW7 gene have these features:
●    Global developmental delay and intellectual disability
    ○    Ranging from borderline to severe
●    Neurological issues
    ○    Hypotonia
    ○    Seizures
    ○    Macrocephaly
●    Gastrointestinal issues
    ○    Feeding difficulties
    ○    Constipation
●    Variable brain structural abnormalities (on CT and MRI)
    ○    Absent, hypoplastic or dysplastic corpus callosum
    ○    Abnormal cerebellum
    ○    Delayed myelination
    ○    Thick brainstem
    ○    Polymicrogyria
    ○    Scattered small subcortical calcifations

Uncommon features in individuals:
●    Ophthalmological features such as strabismus and abnormality of refraction
●    Ataxia
●    Microcephaly, although more commonly macrocephaly
●    Abnormal palatal, uvular or laryngeal morphology
●    Cardiac anomalies
●    Cryptorchidism
●    Neutropenia

There are no recognisable facial features, however some individuals had features of:
●    Deeply set eyes with upper eyelid fullness
●    Cleft or high palate
●    Midface retrusion with class III malocclusion
●    Tall or broad forehead
●    Cutaneous Blaschkoid dyspigmentation